Introduction: The agenesis of sphenoidal sinus in adults is a rare condition, while the frontal sinus hypoplasia or agenesis is more frequently seen. Although both the earlier mentioned conditions together are extremely rare. The sphenoid sinuses can be identified in the fetus at 4 months and after 3 years. By the age of 7 years, sphenoid sinuses extend to the sella turcica. By the age of 12 years, the sphenoid pneumatization reaches its final size, although further enlargement into the basisphenoid may occur in the adult. The frontal sinus is the last one to pneumatize, beginning from around the age of 3 years and ending after the age of 18 years.